Myeloproliferative neoplasms (MPNs)
Overview
- Definition: clonal hematopoietic stem-cell disorders with effective proliferation of one or more myeloid lineages (RBC, WBC, platelet) driven by activated tyrosine kinase signaling, with preservation of relatively normal terminal maturation and increased peripheral blood counts.
- Classic Philadelphia-negative MPNs: polycythemia vera (PV), essential thrombocythemia (ET), primary myelofibrosis (PMF), with variable risk of thrombosis, bleeding, and fibrotic/blastic transformation.
- Philadelphia-positive: CML (see separate note). Other: chronic neutrophilic leukemia, chronic eosinophilic leukemia, MDS/MPN overlap (separate category): CMML, aCML (WHO5: MDS/MPN with neutrophilia), MDS/MPN-RS-T (WHO5: MDS/MPN-SF3B1-T), MDS/MPN-U (WHO5: MDS/MPN-NOS).
- Pathophysiology: constitutive activation of JAK-STAT signaling produces cytokine-independent myeloid proliferation. JAK2 V617F lies in the pseudokinase domain and causes autoactivation.
At a glance: PV, ET and PMF
| Entity | Diagnosis | Risk | Management | ||||||||
|---|---|---|---|---|---|---|---|---|---|---|---|
| PVPolycythemia vera
Median OS ~14 yr (~24 yr if age <60)
JAK2 ~97%CALR 0MPL 0 |
Major
|
LowAge <60 and no thrombosis history |
All patients: phlebotomy to Hct <45% (CYTO-PV) + aspirin 81 mg daily (BID if refractory vasomotor symptoms); treat CV risk factors. Anticoagulate for active thrombosis. Cytoreduce even when low risk if: poor tolerance or frequent need for phlebotomy, symptomatic or progressive splenomegaly, PLT >1,500 or acquired VWD, progressive leukocytosis, or severe symptom burden. Ropeginterferon is an option in low-risk PV. |
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| HighAge ≥60 or prior thrombosis |
Phlebotomy + aspirin + cytoreduction:
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| ETEssential thrombocythemia
Median OS ~20 yr
~10% to MF, <5% to AML
JAK2 50 to 60%CALR 20 to 25%MPL 3 to 5%Triple neg ~10 to 15% |
Major
|
Very lowAge ≤60, JAK2 wild type, no thrombosis | Observation. Aspirin only if CV risk factors or vasomotor symptoms (avoid if acquired VWD). |
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| LowAge ≤60, JAK2 mutated, no thrombosis | Aspirin 81 mg daily (BID if CV risk factors, if no bleeding). No cytoreduction. |
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| IntermediateAge >60, JAK2 wild type, no thrombosis | Aspirin 81 mg daily if no bleeding. Consider cytoreduction for PLT >1,000 to 1,500, acquired VWD, or symptoms. |
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| HighThrombosis at any age, or age >60 + JAK2 mutated |
Cytoreduction + aspirin (anticoagulate if venous thrombosis):
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| PMFPrimary myelofibrosis
Median OS ~6 yr (wide range by risk)
~10 to 20% to AML at 10 yr
JAK2 50 to 60%CALR 25 to 30%MPL 5 to 10%Triple neg ~5 to 10% |
Major
|
DIPSS-plus
Int-1: 1 pt (mOS 6.5 yr) |
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| Higher riskInt-2: 2 to 3 pts (mOS 2.9 yr) High: ≥4 pts (mOS 1.3 yr) MIPSS70+ v2.0 adds high-risk mutations (ASXL1, SRSF2, EZH2, IDH1/2, U2AF1 Q157); CALR type 1 favorable. |
Evaluate for alloHCT (only curative option). JAK inhibitor by platelet count and anemia:
Splenic RT for refractory splenomegaly or extramedullary hematopoiesis. Investigational: pelabresib, imetelstat, navtemadlin (navitoclax MF development discontinued). |
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| All MPNs can progress: marrow or blood blasts 10 to 19% = accelerated phase; ≥20% = blast phase (secondary AML, poor prognosis). | |||||||||||
General Features
- Growth factor hypersensitivity: demonstrable in vitro colony assays (endogenous/cytokine-independent colonies).
- Epidemiology: collective incidence approx. 2 to 3/100,000/year (PV ~0.8, ET ~1.0, PMF ~0.5); peak frequency in the 5th to 7th decades of life.
- Bone marrow: HYPERCELLULARITY with megakaryocyte hyperplasia or dysplasia.
- Clinical hallmarks: thrombotic/bleeding diathesis; splenomegaly and hepatomegaly; extramedullary hematopoiesis.
- Natural history: spontaneous transformation to myelofibrosis and/or acute myeloid leukemia (AML), especially myelofibrosis.
Driver Mutations & Prevalence
- JAK2 V617F: PV ~95%, ET ~50 to 60%, PMF ~50 to 60%; somatic gain-of-function in exon 14.
- JAK2 exon 12: ~3% of PV (often JAK2 V617F-negative PV); isolated erythrocytosis without ↑ WBC/platelets.
- CALR (calreticulin), exon 9: ET ~20 to 25%, PMF ~25 to 30%; type 1 (52-bp deletion) and type 2 (5-bp insertion). Type 1 confers better prognosis in PMF; CALR is thought to mediate MPL (thrombopoietin receptor) activation via novel binding.
- MPL W515L/K: ET ~3 to 5%, PMF ~5 to 10%; thrombopoietin receptor.
- Triple-negative (no JAK2/CALR/MPL): ~10 to 15% ET, ~5 to 10% PMF, worse prognosis in PMF (often carry other adverse mutations).
- High-molecular-risk (HMR) mutations in PMF: ASXL1, EZH2, SRSF2, IDH1/2 (MIPSS70 and MIPSS70-plus); MIPSS70-plus v2.0 adds U2AF1 Q157. Confer worse prognosis. Used in MIPSS70 and MIPSS70-plus scoring.
- Clonal hierarchy: MPN driver mutations may be preceded by CHIP-like clones; HMR mutations confer worse prognosis especially in PMF.
JAK2 Structure-Function
- The mutation occurs in JH2 (the pseudokinase domain), which normally exerts negative regulation over JH1 (the kinase domain). Loss of this autoinhibition results in constitutive JAK-STAT activation.
Calreticulin (CALR) Biology
- Endoplasmic reticulum (ER) resident protein; provides quality control of protein folding (chaperone function) and binds/stores Ca2+.
- Mutations occur as heterozygous insertions and/or deletions in exon 9.
- ALL mutations cause a +1 bp frameshift leading to a novel C-terminal peptide.
- CALR can be detected by IHC.
Other (Non-driver) Mutations
- While JAK2, CALR, and MPL are the driver events, mutations in other genes, particularly TET2, ASXL1, and DNMT3A, are found in over half of MPN patients.
- Less common: splicing regulators (SRSF2, SF3B1, U2AF1, ZRSR2) and other regulators of chromatin/epigenetics/signaling (EZH2, IDH1, IDH2, CBL, KRAS, NRAS, STAG2, TP53).
- These additional mutations are more frequent in PMF and advanced disease than in PV/ET, and several correlate with poorer prognosis (EZH2, IDH1, IDH2, SRSF2, U2AF1, and ASXL1 in PMF).
WHO 2022 Diagnostic Highlights
- PV: Hb >16.5 (M) / 16.0 (F) g/dL or Hct >49% (M) / 48% (F); BM hypercellularity with trilineage proliferation; JAK2 mutation. Subnormal serum EPO supportive (minor criterion).
- ET: platelets ≥450K, BM with megakaryocyte proliferation (large/mature), exclusion of other MPN/MDS, JAK2/CALR/MPL or other clonality; rule out reactive thrombocytosis.
- PMF: prefibrotic (overt megakaryocytic atypia, no/minimal fibrosis) vs overt (MF-2/3 reticulin/collagen fibrosis, leukoerythroblastic, splenomegaly); WHO 2022 retained both stages.
Common Themes Across MPNs
- Thrombosis: arterial > venous (especially in PV/ET); ~20% have thrombosis at or before diagnosis; splanchnic vein thrombosis (Budd-Chiari, portal vein), always work up for occult MPN even with a normal CBC (JAK2 testing).
- Hemorrhage: especially with extreme thrombocytosis (>1000K) due to acquired von Willebrand syndrome (large vWF multimers cleaved).
- Pruritus (PV, aquagenic), erythromelalgia, splenomegaly, fatigue, B symptoms, cytopenias (especially in MF).
- Transformation: to MF (post-PV/post-ET MF) and to AML (~5 to 20% over 10 to 20 years depending on MPN type and risk factors).
- Risk stratification: thrombosis risk for PV (age ≥60 or prior thrombosis = high risk; conventional criteria only); for ET (IPSET-thrombosis adds JAK2+); for PMF (DIPSS, DIPSS-plus, MIPSS70, MIPSS70-plus Version 2.0, GIPSS).
Treatment Strategies
- PV: phlebotomy to Hct <45%, low-dose aspirin; cytoreduction (hydroxyurea, ropeginterferon, ruxolitinib if HU-intolerant) for high-risk disease.
- ET: aspirin (CV risk-based); cytoreduction (HU, anagrelide [PT-1 trial, HU plus aspirin superior to anagrelide plus aspirin], pegylated interferon).
- PMF: 4 FDA-approved JAK inhibitors, ruxolitinib (1L, 2011), fedratinib (post-rux or 1L, 2019), pacritinib (platelets <50k, 2022), momelotinib (anemia, 2023). Allo-HSCT for fit patients with DIPSS-plus int-2/high or MIPSS70-plus high/very-high.
- Pegylated interferon / ropeginterferon (Besremi, FDA 2021): younger PV/ET; molecular response, may be disease-modifying.
- Aspirin: standard in PV and most ET (per IPSET-thrombosis risk).
- Hydroxyurea: 1L cytoreduction for high-risk PV/ET.
- MF novel combos (2024 to 2025): MANIFEST-2 (pelabresib BET-i plus rux vs rux), SVR35 met (66% vs 35%) but TSS50 NOT met, FDA path uncertain. TRANSFORM-1 (navitoclax plus rux), SVR met but symptoms not, navitoclax MF development discontinued 2024.
- Ropeg-IFN ET approval: FDA Aug 31, 2026 approved ropeginterferon alfa-2b for adults with ET (SURPASS-ET vs anagrelide in HU-resistant/intolerant ET, durable response 43% vs 6%). Deep molecular response and disease-modifying potential in Ph-negative MPNs (PV and ET).
- Rusfertide (hepcidin mimetic, VERIFY ASCO 2025): phase 3 met, 77% clinical responders vs 33% placebo in PV; 73% phlebotomy-free; FDA approved Aug 28, 2026 (Mimrylo) for erythrocytosis in adults with PV.
High-Yield Pearls
- JAK2 V617F in >95% of PV, classic association.
- CALR-mutated ET = lower thrombosis risk than JAK2+ ET (OS advantage not clearly independent of age).
- HMR mutations (ASXL1/EZH2/SRSF2/IDH1-2/U2AF1) drive PMF prognosis.
- Splanchnic vein thrombosis: check JAK2 even with a normal CBC.
- Acquired von Willebrand syndrome: bleeding with extreme thrombocytosis >1000K.
- Allo-HSCT: only curative therapy for MPNs; reserved for DIPSS/MIPSS70+ intermediate-2/high MF, plus selected intermediate-1 with high-risk mutations, unfavorable karyotype, transfusion dependence or excess blasts; risk-stratify post-PV/ET MF by MYSEC-PM; also blast-phase MPN after cytoreduction.
- Ropeginterferon: disease-modifying potential; younger PV.